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The Cost of Oppositional Defiant Disorder and Disruptive Behavior: A Review of the Literature Jacob D. Christenson, D. Russell Crane, Julie Malloy & Shannon Parker Journal of Child and Family Studies ISSN 1062-1024 J Child Fam Stud DOI 10.1007/s10826-016-0430-9 1 23 Your article is protected by copyright and all rights are held exclusively by Springer Science +Business Media New York. This e-offprint is for personal use only and shall not be selfarchived in electronic repositories. If you wish to self-archive your article, please use the accepted manuscript version for posting on your own website. You may further deposit the accepted manuscript version in any repository, provided it is only made publicly available 12 months after official publication or later and provided acknowledgement is given to the original source of publication and a link is inserted to the published article on Springer's website. The link must be accompanied by the following text: "The final publication is available at link.springer.com”. 1 23 Author's personal copy J Child Fam Stud DOI 10.1007/s10826-016-0430-9 ORIGINAL PAPER The Cost of Oppositional Defiant Disorder and Disruptive Behavior: A Review of the Literature Jacob D. Christenson1 • D. Russell Crane2 • Julie Malloy2 • Shannon Parker1 Ó Springer Science+Business Media New York 2016 Abstract This purpose of this paper is to review the literature on the treatment of Oppositional Defiant Disorder, with a specific focus on cost analyses. In general the literature shows that while there has been substantial research on Oppositional Defiant Disorder there has been little focus on the costs involved. A search of the major databases in psychology and the social sciences yielded only seven articles even marginally appropriate for a review of costs associated with Oppositional Defiant Disorder and related disruptive behavior. Interestingly, only two of these studies investigated treatment costs specifically associated with Oppositional Defiant Disorder. These studies showed that the treatment of Oppositional Defiant Disorder is much less expensive than the treatment of Conduct Disorder and family therapy is the most cost effective approach. Overall, the review showed that there is a dearth of literature related to treatment costs, which leads to the conclusion that much more research is needed on the cost of treating Oppositional Defiant Disorder. Keywords Oppositional defiant disorder Costeffectiveness Cost analysis Disruptive behavior & Jacob D. Christenson [email protected] 1 Marriage and Family Therapy, Mount Mercy University, 1330 Elmhurst Dr. NE, Cedar Rapids, IA 52402, USA 2 Marriage and Family Therapy, Brigham Young University, 234 TLRB, Provo, UT 84602, USA Introduction Behavioral disorders place considerable strain on the individual, family, and society (Charles et al. 2011). These childhood disorders are becoming increasingly recognized as an area of major public health concern, with numerous studies reporting an alarmingly high prevalence in the childhood population (Maughan and Rowe 2004; Loeber et al. 2000). One of the most common of these childhood psychiatric disorders is Oppositional Defiant Disorder (ODD). The Diagnostic and Statistical Manual of Mental Disorders [(DSM-V), American Psychiatric Association (APA) 2013] defines ODD as a pattern of angry/irritable mood, argumentative/deviant behavior and vindictiveness that is severe enough to impair the child’s functioning for at least 6 months. Studies on the point prevalence of this disorder estimate the occurrence to be between 2 and 16 %; the numbers varying depending on the population, ascertainment methods, and diagnostic measures used (Loeber et al. 2000). Studies demonstrate that the presence of ODD is associated with lifelong mental health disorders in 50 % of children affected (Boylan et al. 2007). This childhood disorder is of great interest to the mental health professions not only because of the disruption it causes, but also because it is highly predictive of delinquency, criminality, and substance abuse in later adolescence and adulthood (Cohen 1998). Although it is clear treatment of ODD should be a priority, the current health care market dictates treatment must not only reduce symptoms, but also be cost effective as well. Accordingly, the purpose of this article is to outline the current research on the cost of ODD and disruptive behavior. Furthermore, this article will make the argument that the current body of literature is deficient and more research is 123 Author's personal copy J Child Fam Stud needed because of the lack of ODD specific findings. First, the paper will provide some background concerning the state of knowledge as it relates to ODD and its treatment, as well as the implications this has for costs. Second the paper will cover in depth the cost literature. Finally, the paper will focus on the strengths and weaknesses in the literature, as well as what future research is needed. Before delving into the research relating to the cost of ODD and its treatment, it should first be established that a significant amount of research has been conducted on ODD already and relevant findings have implications for costs. Accordingly, this section of the paper is included to briefly touch on information gathered from studies of ODD focusing on age of diagnosis, developmental sequence, and the impact on parents. As is common in this field, articles referenced in this paper generally divide childhood mental illness into two categories, behavioral disorders and emotional disorders. Behavioral disorders are those disorders that include externalized behavior, such as ODD and Attention Deficit Hyperactivity Disorder (ADHD). Emotional disorders parallel internalizing disorders such as depression and anxiety. Diagnosis by Age ODD is described in the DSM-V (APA 2013) as typically being first noticeable during the preschool years and not usually developing after early adolescence. The typicallydeveloping child likewise starts to display oppositional behavior at an early age; however, this normal oppositional behavior tends to diminish as they mature (Mireault et al. 2008). While some children might demonstrate this type of typical oppositionality, other children present with more severe oppositional and defiant behavior. When these behavior problems persist over time they can ultimately become severe enough to warrant clinical attention (Borrego and Burrell 2010). Some young children with ODD ‘‘grow out of it,’’ yet a substantial portion do not. Many children continue to have ODD as a single diagnosis, while others later develop anxiety or depression as a comorbid disorder (Lavigne et al. 2001). The presence of other disorders with ODD can complicate treatment, increasing the number of sessions needed and therefore the total cost of treatment. For these reasons it is important that children with this disorder be treated early before symptoms become more severe. Add to this the fact that externalizing behavior has been found to show considerable stability throughout childhood and adolescence (Webster-Stratton and Taylor 2001; Farris et al. 2011) and it becomes clear that cost-effective treatment methods are needed. As noted above, preschool children showing signs of ODD are likely to continue to exhibit the disorder, and such 123 children often have ADHD as a comorbid concern (Lavigne et al. 2001). ODD in early childhood is predictive of earlyonset conduct disorder (Burke et al. 2010). This is important because early-onset antisocial behavior is linked to serious maladaptive social and health functioning when compared to later-onset antisocial behavior (Odgers et al. 2007). Some researchers have noted that youth showing the childhoodonset subtype of Conduct Disorder (CD) may have had ODD during early childhood (Maughan and Rowe 2004). As such, the onset of ODD represents an important window of opportunity for prevention efforts (Greene and Doyle 1999). Should this window be missed there is a greater likelihood the child’s behavioral problems and emotional problems will become more severe, and severe mental illness is known to burden the health care system and increase costs in the long term (e.g., Insel 2008). Developmental Sequence of Psychopathology Children with oppositional and conduct problems comprise a diverse group who engage in a broad array of problem behaviors ranging from relatively minor defiance and temper tantrums to more serious violations such as physical aggression, destructiveness, and stealing (Cunningham and Ollendick 2010). ODD is generally considered a milder disorder than other more severe behavior disorders such as CD or Antisocial Personality Disorder (APD), but it is far from benign (Frick and Nigg 2012). It has been argued that ODD forms an early stage in CD development and constitutes a developmental antecedent to CD in a significant number of cases (APA 2013). Research on predictive validity shows that a substantial proportion of children with ODD later develop CD, and a proportion of those with CD later meet criteria for APD. Loeber et al. (2002) conducted a study tracking the development of disruptive behaviors and showed that ODD is a strong predictor of CD, and that CD is a strong predictor of APD. This same study found a correlation between individuals with CD and APD in terms of callous/unemotional behavior. When callous/unemotional behavior is present at an early age it may be more likely that the child’s behavior will develop into CD or APD. This is in contrast to those who may develop the disorder in response to poor parenting or inadvertent reinforcement of negative behaviors (Frick et al. 1992). Studies suggest that ODD and CD are different disorders but are developmentally related (Greene and Doyle 1999). Although longitudinal studies have consistently found that ODD symptoms are associated with increases in CD symptoms over time, it is clear that not all children with ODD will go on to develop CD (Loeber et al. 2009). However, according to researchers, if left untreated, about 52 % of children with ODD will continue to meet the criteria up to 3 years later and about half of those will later progress into Author's personal copy J Child Fam Stud CD. The costs associated with CD and APD are significant. Foster and Jones (2005) reported that over a 7 year period the additional public costs associated with CD was $70,000. Cohen and Miller (1998) estimated that the cost of psychotherapy for victims of crime, which is often committed by individuals with APD, was more than $5.8 billion in a year. Such findings again support the notion that early treatment of ODD should be associated with overall cost savings since there is an opportunity for prevention of more serious conditions that have a much greater impact on costs. Impact on Parents Consistent with previous literature, one study by Evans, Sibley, and Serpell (2009) affirms that defiance and delinquency are very wearing on parents. Childhood oppositional and defiant behaviors are one of the greatest contributors to parent stress (Angold et al. 1999; Evans et al. 2009; Pfiffner et al. 2005; Seipp and Johnston 2005). Stress has long been understood to be a significant contributor to health care costs and some estimate that up to 90 % of all doctor visits are due to stress and stress related symptoms (e.g., Gibson 1993). A decrease in stress related doctor visits by parents of children with ODD could result in a significant cost savings. This diagnosis is particularly detrimental to parental mental health (Burke et al. 2002). In one study, a diagnosis of ODD emerged as the most significant predictor of caregiver strain (Bussing et al. 2003). Several other studies have established that parents of children with externalizing disorders show significantly elevated levels of caregiver distress related to their child’s disorder (Kashdan et al. 2004). Parental stress has been shown to lead to other mental health disorders such as depression (Sim and England 2009). The potential negative effects of ODD on parental mental health is another factor that could be associated with increased costs. Due to the relationship between parent and child mental health, it is possible that treating ODD might also result in cost savings associated with improved parental functioning (e.g., increased work productivity). Therapeutic Interventions Over the last several years, interest in the economic analysis of interventions and services to prevent or treat behavioral problems among children has grown (Foster and Murrihy 2011). Treatment for ODD and CD is most often not specific to either disorder, but to conduct problems or antisocial behavior in general. There are various empirically supported treatments (ESTs) that can help to reduce symptoms of childhood behavioral disorders. Most methods of treatment for these problems fall under either an individual or family modality and both forms have proved successful and positively impact treatment outcomes (e.g., Crane and Payne 2011). The treatment strategies that have been found to be most effective employ cognitive behavioral strategies while targeting multiple levels, most commonly child and parent, but also may include family, peers, and the school (Loeber et al. 2009). One interesting study found that the use of dialectic behavioral therapy may also be useful in reducing symptoms of ODD as well (Nelson-Gray et al. 2006). Psychological interventions specifically for the family such as parenting skills training and behavior therapy have been found to reduce conflict behaviors in children with ODD (Kelsberg and St. Anna 2006). Therapy can serve as a preventative intervention for children with behavioral problems by supporting parents in the acquisition of strategies to promote positive behaviors (Charles et al. 2011). There is evidence from randomized trials that suggests parent management training strategies are effective in the treatment of disruptive behavior disorders as well (Burke et al. 2002) Medication management is another option for treatment, though at this point it is usually seen as an adjunct to behavioral interventions. Most often medication is used to primarily treat another comorbid disorder such as ADHD, and the benefits of this primary intervention is seen as then extending to symptoms of ODD (Newcorn et al. 2005; Steiner and Remsing 2007). Nevertheless, in at least one study, treatment with divalproex sodium resulted in better management of symptoms when CD was the primary diagnosis (Steiner et al. 2003). Although this study was conducted on those with CD, the results lend support to the idea that medication can be helpful. However, Steiner and Remsing (2007) recommend that medications only be used for the management of ODD after a strong therapeutic alliance has been establish and assent has been obtained from the client. Inclusion of Family Component Considering the family’s important role in the initiation and escalation of childhood behavior problems, familybased interventions have been of great interest to treatment researchers and community **practitioners (e.g., Sexton et al. 2004). It should be noted that while the child’s behavior can be very distressing for the parents, parental factors (e.g., APD tendencies in the parents) can also have a significant effect on the development and course of ODD in their children (Frick et al. 1992). Therefore, it is not surprising that several reviews have found family-based systemic treatments to be model approaches for youth with conduct problems (Henggeler and Sheidow 2003; Kazdin and Weisz 1998). Family-focused therapy addresses several aspects of a child’s environment including individual internal processes, family relations, caregiver functioning, 123 Author's personal copy J Child Fam Stud peer relations, and the school environment among others (Crane et al. 2005). Previous studies have shown that family therapy is effective at reducing symptoms of ODD (Carr 2009). Unfortunately, little research has been done on treatment outcomes and cost of this specific behavioral disorder, let alone how treatment might reduce health care costs for ODD patients and their families. Given the research demonstrating that a significant amount of a child’s noncompliant and inappropriate behavior is shaped and maintained through maladaptive patterns of family interaction, treating the problem as a family modality is likely to be more effective than other forms of treatment. One of the tenants of a family systems approach is that a change in one area of the system will results in a change in other parts of the system. This would lead to the conclusion that improvement in the identified patient may result in improvement in parents and siblings as well. As an example, Law and Crane (2000) demonstrated that when the identified patient (i.e., the child) was treated, family members reduced their own health care use by 30.5 %. This type of reduction in health care use could result in significant cost savings that extend beyond the treatment of the child. Unfortunately, the literature on ODD as highlighted above, while rich in content is extremely short on information related to costs. This is in contrast to other childhood behavioral disorders that have received significant attention in the cost literature. For example, Matza, Paramore, and Prasad (2005) conducted an extensive review on the costs associated with ADHD and were able to find 22 relevant articles. In terms of actual costs, the Centers for Disease Control and Prevention (CDC) (2016) cite a number of studies that demonstrate costs associated with ADHD are well known. Among the statistics they cite are that the annual cost of ADHD is between $12,005 and $17,458 per individual and the total societal cost of ADHD in 2000 exceeded $31.6 billion. The CDC also indicated that at least one study has shown that annual costs for an adult with ADHD are approximately three times higher than for an individual without ADHD. As will be evident below, the literature on ODD is not as well developed. Review of Costs In order to find articles related to costs associated with ODD, major databases from psychology and the social sciences were searched using EBSCOhost. Articles from all years available in the databases were included. The databases used for this study included Academic Search Complete, Academic Search Elite, PsycARTICLES, PsycINFO, SocINDEX, eBook Collection (EBSCOhost), Newswires, and eBook Academic Collection (EBSCOhost). Broad search 123 terms were used to find studies on ODD because of the paucity of research specifically focused on costs associated with this disorder. The search terms used were cost effectiveness, cost, cost analysis, budget, financial, health care cost and Oppositional Defiant Disorder. This search resulted in a total of 109 articles, but of these only seven articles specifically mentioned costs associated with the treatment of ODD. Given the few studies found, all studies that included specific data generated by the researchers were included in the review. Of these seven articles, only one article reported numerical data appropriate for this review. Because of the few studies found using ODD as the key term, the search was expanded to include studies on costs associated with ‘‘disruptive behavior.’’ This second search was conducted to delve deeper into the literature, and because of the tendency of researchers to lump ODD in with other disorders when evaluating costs. As can be seen below, a number of the studies found in this second search actually contained specific information on costs associated with ODD. For the second search, only cost analysis and cost effectiveness were used as secondary terms in order to generate more applicable results. In the search using disruptive behavior as the key term, 248 articles were found in the initial search, with 11 articles specifically highlighting costs related to disruptive behavior. Of these 11 articles, only 5 reported specific numerical data related to costs. Finally, an unpublished thesis that also reported on specific costs associated with the treatment of ODD was included. The total number of papers found, selected, and reviewed was seven (Table 1). Public Costs The public costs of behavior problems among children and youth are enormous (Foster and Jones 2005). This disorder is associated with substantial emotional and financial burdens to individuals, families, schools, agencies, and society at large (Farris et al. 2011). One estimate is that $1.7 to $2.3 million can be saved from successful intervention for each high-risk youth by avoiding a lifetime of negative impacts from disruptive and/or delinquent behavior (Cohen 1998). Studies demonstrate that in general there is a small subset of offenders who commit a large share of criminal offenses (Cohen and Piquero 2009). It would seem plausible that if these offenders can be accurately identified early and provided with preventative treatment criminal activity may be curtailed. While not specific to ODD, such information about offenders highlights the potential value of targeting high-risk youth presenting with ODD or CD (Cohen and Piquero 2009). The results of the literature search returned only one article that reported public costs specifically associated Author's personal copy J Child Fam Stud Table 1 Studies considered regarding costs associated with Oppositional Defiant Disorder Study Foster and Jones (2005) N 664 Ages Gender Ethnicity/race Behavioral issues Method Data available Key results 11–18 M/F AA, 49 % At risk youth with CD or ODD diagnosis Longitudinal Public costs and treatment costs 7-Year public cost, [$23,000 Emotional/ behavioral disorders Retrospective survey Medical expenditures Annual ODD expenditure, $2196 NR Normal/ abnormal SDQ scores Cross sectional Medical expenditures Average cost difference, €1237 NR NR Cost effectiveness Treatment costs and startup costs Per child, $1025 C, 48 % L/A, 3 % Guevara et al. (2003) 3955 Kohlboeck et al. (2014) 3579 Goldfine et al. (2008) 17 Studies 2–18 M, 65 % F, 35 % C, 80 % AA, 12 % L, 8 % M, 51 % F, 49 % Thompson et al. (1996) 66 Robinson et al. (1996) Malloy (2014) 10 2–8 NR treatment cost, [$13,000 startup, $14,063 2–17 M, 64 % C 97 % Conduct problems Nonequivalent control group Treatment costs Per family, $70 45 5–12 F, 36 % M/F NR Behavioral problems Program description Treatment costs Per day, $41 9904 3–16 M, 65 % NR ODD Cost effectiveness Medical claims First episode of care, $390 F, 35 % NR not reported, AA African American, A Asian, L Hispanic/Latino, C Caucasian, M male, F female with ODD. Foster and Jones (2005) reported findings from the Fast Track Project, which included 664 children at risk for behavioral problems, tracked over 7 years. The focus of the article was on the cost of CD, but the authors reported specific comparison information from a subsample with ODD. Costs resulted from the youths’ involvement in a variety of child-serving sectors; namely, juvenile justice, child welfare, and special education (Foster and Jones 2005). The figures they reported show that the overall public cost was almost twice as much for those diagnosed with CD compared to those diagnosed with ODD. Over the 7 year period the total public cost of CD was more than $41,000 and the total public cost of ODD was more than $23,000. At risk youth in an undiagnosed comparison group had much lower public costs, which for this group was more than $11,000. Public costs generally increased over the course of the study. In the first year the total public cost was $2929 for CD, $2072 for ODD, and $1009 for the comparison group. By the seventh year of the study these costs had risen to $6178 for CD, $3271 for ODD, and $1704 for the comparison group. Over the course of the 7 years, the average annual public cost was $6735 for CD, $4033 for ODD, and $3830 for the comparison group. Those in the 90th percentile for costs accounted for roughly half of all expenditures. For those in this percentile, the average yearly expenditures were $25,985 for CD, $12,848 for ODD, and $8212 for the comparison group. The strengths and weaknesses of the Foster and Jones article will be discussed in the section on ODD specific studies below. ‘‘Disruptive Behavior’’ Studies As noted above, five studies were found that included cost data when the primary search term was disruptive behavior. Although these studies do not provide substantive information about ODD, they do provide information about costs associated with ODD behaviors and treatments. Guevara et al. (2003) conducted a study using data from the 1996 Medical Expenditure Panel Survey with the intent of determining if children with behavioral disorders had similar health care expenses to children with physical conditions. The authors included a number of ICD-9 codes representing a wide range of emotional and behavioral disorders (including ODD, CD, and ADHD) when deriving their sample of 3955 children. Guevara et al.’s (2003) study showed that children with behavioral disorders had significantly higher expenditures ($1468) than control children with no conditions ($710). However, when compared to children with physical disorders ($1071) the costs were not significantly higher. When looking at subtypes of services, children with behavioral disorders were also found to have significantly higher expenditures for office visits ($425 vs $236), prescription medications ($235 vs $156), and emergency room visits ($155 vs $61) when compared to children with 123 Author's personal copy J Child Fam Stud physical disorders. When the authors adjusted costs based on demographics and physical comorbidities they also found that those with emotional disorders had total expenditures that were twice what was found for behavioral disorders. Interestingly, these authors also compared sub-groups and actually found that expenditures for those with ODD ($2196) were significantly higher than for those with CD ($1172) or ADHD ($1093); however, these authors argue that caution should be exercised in interpreting this result since it was based on a small subset of the sample and they did not adjust for other factors that would have affected this finding. Although it is positive that a national sample was used, one significant weakness of Guevara et al.’s (2003) study was that the data was limited to medical expenditures and the authors were unable to distinguish mental health treatment from regular medical use. Accordingly, the authors really have nothing to offer regarding the cost of mental health treatment. It is possible that treatment would actually reduce the costs for those with a particular disorder if they engaged in treatment. Conversely, engaging in treatment might also result in increased costs if treatment costs were added on top of the regular medical expenditures. However, without data on treatment it is only possible to say that one group had higher costs, not why they had higher costs. This lack of a focus on treatment was a weakness in almost all studies that were found. Finally, Guevara et al. relied on parent’s reports of symptoms for making a diagnosis, which makes their categorizations potentially unreliable. Kohlboeck et al. (2014) used data from a 10-year follow-up of the German Infant Nutritional Intervention study to determine health care cost for children with elevated scores on the Strengths and Difficulties Questionnaire (SDQ). According to Kohlboeck et al. the SDQ is designed to aid in identify children who are at risk of a psychiatric disorder. Based on normative data, the authors were able to categorize participants as ‘‘normal,’’ ‘‘at risk,’’ ‘‘borderline,’’ and ‘‘abnormal.’’ Costs among the participants in these groups were then analyzed. They compared children with these higher levels of difficulties to children with normal difficulties across a 12-month period. This survey provided information on the type of difficulties (i.e., attention, emotional, conduct, etc.) and types of health care used (e.g., psychotherapy). These authors found there was a highly significant cost difference (p \ .001) for children in the abnormal range, which was on average €1237 ($1340) more than for children with normal difficulties. Much of this cost difference was attributable to higher hospitalization costs for those with abnormal difficulties. When the subtypes of difficulties were investigated, these authors found the average medical expenditures for those with conduct problems (€190; $215) was significantly lower than the costs for either those with emotional symptoms 123 (€603; $682) or hyperactivity/inattention (€391; $442). Psychotherapy costs were similar for all three groups, and those with emotional symptoms on average had significantly higher inpatient rehabilitation costs than those with conduct problems (€83; $94 vs €0; $0). The questions on the SDQ conduct problem subscale are more closely aligned with ODD than CD (e.g., questions related to temper tantrums and disobedience). Kohlboeck et al.’s (2014) findings, therefore, support the narrative that treatment for ODD is similar to, or lower, than treatment for other disorders. However, this study also had a significant issue with dropout among those with behavioral disorders. These types of disorders are typically associated with increased use of health care services, which means their calculations may have underestimated the costs for those with behavioral issues. Also, similar to Guevara et al. (2003), this study relied on a screening measure instead of a diagnostic assessment to determine the presence of disordered behavior. Goldfine et al. (2008) conducted a cost-effectiveness study on Parent–Child Interaction Therapy (PCIT). Although PCIT is used for more than the treatment of disruptive behaviors, this study was included because the authors specifically focused on disruptive behaviors in their paper. The authors used 17 studies to determine effectiveness, while estimating costs associated with starting up and running the program. The total cost per child that participates in the program was found to be $1025, and the startup cost was $14,063. When cost ratios were calculated, Goldfine et al. found that a one point decrease on the Eyberg Child Behavior Inventory cost between $22 and $87, on the Child Behavior Checklist it was $101, and on the Parenting Stress Index it was $26. Before detailing the next study, it should also be noted that Aos et al. (2004) reported on PCIT in their study of delinquency as well and found that the benefits outweighed the costs by $3427. Aos et al. is not reviewed in detail here because of its specific focus on delinquency. Of the articles reviewed thus far, Goldfine et al. (2008) stand out as an exemplar in terms of cost study methodology. These authors use multiple sources of data to determine costs and include both direct and indirect costs in their calculations. Additionally, they used accepted formulas for calculating cost-effectiveness and reported evidence of the treatment’s effectiveness, unlike the other studies reviewed in this paper. The only significant weakness of the study is that the authors used secondary data to make their calculations, which required that the authors make estimations of costs in some areas (e.g., cost of office space), as opposed to using actual incurred costs from a specific program. The last two studies found using disruptive behavior as a search term both has serious issues in terms of methods or data available. The study by Thompson et al. (1996) indicated in the title that the article reported on a cost- Author's personal copy J Child Fam Stud effectiveness evaluation of a parent training program. However, the authors failed to consider anything beyond staff costs in their estimates and did not report any cost ratios. Because of the lack of a thorough assessment of costs any calculations with this data would result in significant underestimation. The authors only reported that by shortening the program they were able to reduce the cost from $160 per family to $70 per family. While it is noteworthy that costs were reported at all, the study had the potential to make a much larger contribution to the literature than what was realized. Robinson et al. (1996) reported on a partial day program serving youth with behavioral disorders. These authors did not purport to be conducting a cost-effectiveness study, though they did report on the cost of the program. They noted that the cost per day per child was $41, which was much less than the $300–$500 rate for hospitalizations per day. However, without data about the outcomes of the program it is impossible to determine if one was more cost-effective than the other. ODD Specific Studies Two studies were found that had substantive information concerning the cost of treating ODD specifically. The first of these, Foster and Jones (2005), has already been cited above with regard to public costs. These authors also reported on treatment costs for CD, ODD, and a comparison group. Treatment costs were more than three times as much for those diagnosed with CD compared to ODD. Over the 7 year study period the total treatment cost was more than $43,000 for CD and $13,000 for ODD. The undiagnosed comparison had much lower treatment costs (just over $7000), and this amount was closer to the figures for ODD. As was the case for public costs, treatment costs generally increased over the course of the study. In the first year the treatment costs were $2648 for CD, $652 for ODD, and $450 for the comparison group. By the seventh year these costs were $12,504 for CD, $1830 for ODD, and $1517 for the comparison group. By far, the greatest cost for any of the groups was because of inpatient mental health care. The total spent on this type of treatment over the course of the study was $24,089 for CD, $5988 for ODD, and $3115 for the comparison group, on average. The study by Foster and Jones (2005) had a number of strengths and weaknesses. One of the primary strengths of the study was the use of multiple sources of data to determine costs. The researchers looked at school and court records, and conducted interviews with the children and their families. Additionally, they looked at numerous types of service use, including general health care, inpatient hospitalization, emergency room visits, residential treatment, etc. Using multiple sources of data strengthens cost analysis (Christenson and Crane 2014). The authors also used actual diagnostic measures to categorize the participants, as opposed to symptom checklists. In terms of weaknesses, Foster and Jones used the same per-unit cost for residential settings, even though the settings where CD is treated may be much more expensive. This means that they may have underestimated the relative cost of treating CD. The also authors relied on self-report for health care utilization, which may have led to underreporting and underestimating costs. In terms of cost-analysis methodology, the greatest weakness of their study is that they did not consider the benefits of treatment, which makes it impossible to estimate costs versus benefits. The second study concerned the cost effectiveness of services for ODD delivered by different provider types and using different treatment modalities (Malloy 2014). This study looked at discrete episodes of care (i.e., sequence of services provided without a 90 day break) and found that that first episode of care cost on average $390 dollars. Counselors had the lowest average cost ($340) and medical doctors had the highest average cost ($450) per episode of care. The study also looked at which modality was the most cost effective (i.e., individual, family, or mixed) and found that family therapy was the most cost effective, though this was also the least used. The author also tested whether treatment costs would differ according to age or gender and found no significant differences. Malloy’s (2014) study had a large, national sample of individuals diagnosed with ODD, which is a significant strength. The study is also the only one that looked at the costs associated with different modalities and provider types. The most glaring weakness of this study is the lack of established methodology to calculate cost-effectiveness. The cost-effectiveness formula used by the author is not recognized in the cost-effectiveness literature, though it does provided a common denominator with which different providers and modalities can be compared. Accordingly, one can’t conclude that a typical episode of care costs $390 since the episode didn’t end until they didn’t have a session for over 90 days, which means in some cases this episode extended over multiple years, which cannot be considered a typical length of treatment. Summary and Future Research This review clearly shows that little research has been done on the cost-effectiveness of ODD treatment, and that when ODD is isolated from CD the cost of treatment may be much lower, though of course this may be impractical given such high comorbidity with other disorders. The review also shows that costs associated with conduct problems in general may be significantly lower than those 123 Author's personal copy J Child Fam Stud associated with emotional concerns, and are actually similar to what would be expected for youth suffering from physical disorders. In all cases, inpatient mental health care is much more expensive than other forms of treatment, and it is plausible that those with emotional problems or CD would be much more likely than those with ODD to be treated in such settings, which lends support to the idea that the treatment of ODD should be much lower overall. Unfortunately, although the sample sizes were generally large and fairly representative, the available data makes firm conclusions about costs impossible given the paucity of available data. As indicated in the introduction one of the purposes in conducting this review was to demonstrate the need for more research in this area by shining a light on the dearth of relevant findings. There are a number of weaknesses in the studies review in this paper. Globally, the most pressing of these is that with the exception of Goldfine et al. (2008) none of the studies actually focused on a treatment for ODD or disruptive behavior. Instead the studies looked at the costs individuals with these concerns incur, which is not the same as costbenefit analysis, as will be described more fully below. It is also possible the cost of treating the behavioral problems identified in the studies may actually be underestimated. This is especially true for those studies that only considered general costs, since it is impossible to know what portion was attributable to treatment (or lack thereof) of a psychiatric disorder. In at least one study those with behavioral issues were more likely to drop out (Kohlboeck et al. 2014), which may have led to greater costs associated with this group being excluded in the analysis. Another weakness across studies was the lack of rigorous assessments to determine if the participants actually met the criteria for a specific diagnosis. Furthermore, with the exception of Foster and Jones (2005) none of the studies were longitudinal and mostly relied on retrospective analyses. In general, the studies also lacked rigor in their determination of costs. For example, Thompson et al. (1996) only took into account staffing costs and entirely ignored other direct and indirect costs that are commonly measured in economic evaluations. Finally, none of the studies reviewed deliberately included benefits in their evaluations. As was true for Aos et al. (2004), it is likely that if benefits were included there would be a net savings associated with treatment. More rigorous research is certainly needed to address some of these limitations in the cost literature. As noted, with the exception of Goldfine et al. (2008), none of the studies described above used accepted costbenefit methodology. In order to strengthen the cost literature concerning ODD, researchers need to consider all three core components of this type of research outlined by Christenson and Crane (2014). These authors outline the need for data regarding costs, benefits, and effectiveness (i.e., treatment 123 outcomes). In the current review, effectiveness was the most glaring omission in almost all of the studies. This is unfortunate given there are a number of ESTs for ODD related behaviors. Without an effective treatment to evaluate, true cost-benefit analysis is meaningless, as was the case with the Robinson et al. (1996) article. When referring to costs, Christenson and Crane describe this as the costs of delivering a particular treatment, both direct and indirect. Benefits on the other hand, typically refers to cost savings associated with the treatment. Foster and Jones (2005) provided information that could be used in this type of benefit analysis. They calculated a number of costs that could be prevented if effective treatment were delivered, which could then be considered a benefit if a particular treatment led to a reduction in these types of costs. Costs and benefits once monetized can then be used to calculate the value of a particular program. Often, the monetized benefits far outweigh the costs associated with delivering the program. This type of analysis is what is needed to fill the gap in the literature. Additionally, despite the increasing prevalence and significant costs of behavioral disorders, very little research has assessed cost-effectiveness of family interventions for this population. Little research has also been done on recidivism or dropout rates for children and adolescents with Oppositional Defiant Disorder. There is a need for additional research to help understand variables that may influence a client returning for additional treatment. Effective treatments are critical to help minimize these costs and to help provide adequate support to all who are impacted by the disorder. Further research is required in order to answer questions related to the costs associated with treatment, and as noted above there exists a need to include the benefits beyond just decreased symptoms, such as improving family process and/or quality of life for significant others. 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